Arterial thoracic outlet syndrome (TOS) is a rare condition most frequently observed in relatively young, active, and otherwise healthy individuals. The most typical form involves compression of the subclavian artery within the scalene triangle at the level of the first rib. This usually occurs in conjunction with a congenital cervical rib or first rib anomaly. Similar clinical findings can develop from lesions in the distal axillary artery or its immediate branches, also caused by extrinsic compression, thereby representing a variant of arterial TOS. Compressive lesions of the axillary artery are rare but have been reported in overhead athletes such as baseball pitchers and volleyball players, and seems to be related to the pectoralis minor muscle as in this case.